eprintid: 10205711 rev_number: 7 eprint_status: archive userid: 699 dir: disk0/10/20/57/11 datestamp: 2025-03-07 11:41:49 lastmod: 2025-03-07 11:41:49 status_changed: 2025-03-07 11:41:49 type: article metadata_visibility: show sword_depositor: 699 creators_name: Tosoni, Beatrice creators_name: Naghshineh, Eisa creators_name: Zanin, Irene creators_name: Gallina, Irene creators_name: Di Pietro, Lorenzo creators_name: Cleris, Loredana creators_name: Nadai, Matteo creators_name: Lecchi, Mara creators_name: Verderio, Paolo creators_name: Pratesi, Pietro creators_name: Pasquali, Sandro creators_name: Zaffaroni, Nadia creators_name: Neidle, Stephen creators_name: Folini, Marco creators_name: Richter, Sara N title: The G-quadruplex experimental drug QN-302 impairs liposarcoma cell growth by inhibiting MDM2 expression and restoring p53 levels ispublished: pub divisions: UCL divisions: B02 divisions: C08 divisions: D10 note: Copyright © The Author(s) 2025. Published by Oxford University Press on behalf of Nucleic Acids Research. This is an Open Access article distributed under the terms of the Creative Commons Attribution License (https://creativecommons.org/licenses/by/4.0/), which permits unrestricted reuse, distribution, and reproduction in any medium, provided the original work is properly cited. abstract: Well-differentiated/dedifferentiated liposarcomas (WD/DDLPSs) account for ∼60% of all liposarcomas. They have a poor prognosis due to limited therapeutic options. WD/DDLPSs are characterized by aberrant expression of mouse double minute 2 (MDM2), which forms G-quadruplexes (G4s) in its promoter. Here, we investigated the possibility of targeting WD/DDLPSs with small molecules against the MDM2 G4s. Among the molecules tested, the naphthalene diimide derivative QN-302 significantly impaired WD/DDLPS cell growth and its activity strikingly paralleled cell-specific G4 abundance as measured by CUT&Tag and RNA sequencing analysis. QN-302 stabilized MDM2 G4s at the P2 inducible promoter and prevented polymerase progression from the constitutive P1 promoter, thereby inhibiting the formation of full-length MDM2 transcripts. This resulted in the accumulation of p53 through the p53-MDM2 autoregulatory feedback loop, ultimately leading to apoptotic cell death. In patient-derived xenograft mouse models, QN-302 treatment reduced tumour volume distribution and was well tolerated. We have identified a novel and effective therapeutic strategy to reduce MDM2 expression and promote p53 reactivation in tumours harbouring wild-type TP53, such as WD/DDLPSs. date: 2025-02-28 date_type: published publisher: OXFORD UNIV PRESS official_url: https://doi.org/10.1093/nar/gkaf085 oa_status: green full_text_type: pub language: eng primo: open primo_central: open_green verified: verified_manual elements_id: 2361726 doi: 10.1093/nar/gkaf085 medium: Print pii: 8010959 lyricists_name: Neidle, Stephen lyricists_id: SNEID18 actors_name: Harris, Jean actors_id: JAHAR68 actors_role: owner funding_acknowledgements: 2025 [AIRC] full_text_status: public publication: Nucleic Acids Research volume: 53 number: 4 article_number: gkaf085 pages: 17 event_location: England issn: 0305-1048 citation: Tosoni, Beatrice; Naghshineh, Eisa; Zanin, Irene; Gallina, Irene; Di Pietro, Lorenzo; Cleris, Loredana; Nadai, Matteo; ... Richter, Sara N; + view all <#> Tosoni, Beatrice; Naghshineh, Eisa; Zanin, Irene; Gallina, Irene; Di Pietro, Lorenzo; Cleris, Loredana; Nadai, Matteo; Lecchi, Mara; Verderio, Paolo; Pratesi, Pietro; Pasquali, Sandro; Zaffaroni, Nadia; Neidle, Stephen; Folini, Marco; Richter, Sara N; - view fewer <#> (2025) The G-quadruplex experimental drug QN-302 impairs liposarcoma cell growth by inhibiting MDM2 expression and restoring p53 levels. Nucleic Acids Research , 53 (4) , Article gkaf085. 10.1093/nar/gkaf085 <https://doi.org/10.1093/nar%2Fgkaf085>. Green open access document_url: https://discovery.ucl.ac.uk/id/eprint/10205711/1/The%20G-quadruplex%20experimental%20drug%20QN-302%20impairs%20liposarcoma%20cell%20growth%20by%20inhibiting%20MDM2%20expression%20and%20restoring%20p53%20le.pdf