%I American Association for the Advancement of Science (AAAS) %L discovery10193867 %D 2024 %O This version is the author accepted manuscript. For information on re-use, please refer to the publisher’s terms and conditions. %T Pharmacological modulation of septins restores calcium homeostasis and is neuroprotective in models of Alzheimer's disease %X Abnormal calcium signaling is a central pathological component of Alzheimer's disease (AD). Here, we describe the identification of a class of compounds called ReS19-T, which are able to restore calcium homeostasis in cell-based models of tau pathology. Aberrant tau accumulation leads to uncontrolled activation of store-operated calcium channels (SOCCs) by remodeling septin filaments at the cell cortex. Binding of ReS19-T to septins restores filament assembly in the disease state and restrains calcium entry through SOCCs. In amyloid-β and tau-driven mouse models of disease, ReS19-T agents restored synaptic plasticity, normalized brain network activity, and attenuated the development of both amyloid-β and tau pathology. Our findings identify the septin cytoskeleton as a potential therapeutic target for the development of disease-modifying AD treatments. %K Animals, Humans, Mice, Alzheimer Disease, Amyloid beta-Peptides, Calcium, Calcium Channels, Calcium Signaling, Cytoskeleton, Disease Models, Animal, Homeostasis, Neuronal Plasticity, Neuroprotective Agents, Septins, tau Proteins %V 384 %A Katrien Princen %A Tom Van Dooren %A Marit van Gorsel %A Nikolaos Louros %A Xiaojuan Yang %A Michael Dumbacher %A Ilse Bastiaens %A Kristel Coupet %A Shana Dupont %A Eva Cuveliers %A Annick Lauwers %A Mohamed Laghmouchi %A Thomas Vanwelden %A Sofie Carmans %A Nele Van Damme %A Hein Duhamel %A Seppe Vansteenkiste %A Jovan Prerad %A Karolien Pipeleers %A Olivier Rodiers %A Liese De Ridder %A Sofie Claes %A Yoni Busschots %A Lentel Pringels %A Vanessa Verhelst %A Eveline Debroux %A Marinka Brouwer %A Sam Lievens %A Jan Tavernier %A Melissa Farinelli %A Sandrine Hughes-Asceri %A Marieke Voets %A Joris Winderickx %A Stefaan Wera %A Joris de Wit %A Joost Schymkowitz %A Frederic Rousseau %A Henrik Zetterberg %A Jeffrey L Cummings %A Wim Annaert %A Tom Cornelissen %A Hans De Winter %A Koen De Witte %A Marc Fivaz %A Gerard Griffioen %C United States %J Science %N 6699