eprintid: 10163062
rev_number: 10
eprint_status: archive
userid: 699
dir: disk0/10/16/30/62
datestamp: 2023-01-12 16:52:24
lastmod: 2023-01-12 16:52:24
status_changed: 2023-01-12 16:52:24
type: article
metadata_visibility: show
sword_depositor: 699
creators_name: Lidstone, Sarah C
creators_name: Costa-Parke, Michael
creators_name: Robinson, Emily J
creators_name: Ercoli, Tommaso
creators_name: Stone, Jon
creators_name: FMD GAP Study Group, 
title: Functional movement disorder gender, age and phenotype study: a systematic review and individual patient meta-analysis of 4905 cases
ispublished: pub
divisions: UCL
divisions: B02
divisions: C07
divisions: D07
divisions: F84
keywords: Functional neurological disorder, meta-analysis, systematic reviews, Conversion Disorder, Dystonia, Female, Humans, Movement Disorders, Phenotype, Tremor
note: This version is the author accepted manuscript. For information on re-use, please refer to the publisher’s terms and conditions.
abstract: Functional movement disorder (FMD) is a common manifestation of functional neurological disorder presenting with diverse phenotypes such as tremor, weakness and gait disorder. Our current understanding of the basic epidemiological features of this condition is unclear. We aimed to describe and examine the relationship between age at onset, phenotype and gender in FMD in a large meta-analysis of published and unpublished individual patient cases. An electronic search of PubMed was conducted for studies from 1968 to 2019 according to Preferred Reporting Items for Systematic Reviews and Meta-Analyses guidelines. Individual patient data were collected through a research network. We described the distribution of age of onset and how this varied by gender and motor phenotype. A one-stage meta-analysis was performed using multilevel mixed-effects linear regression, including random intercepts for country and data source. A total of 4905 individual cases were analysed (72.6% woman). The mean age at onset was 39.6 years (SD 16.1). Women had a significantly earlier age of onset than men (39.1 years vs 41.0 years). Mixed FMD (23.1%), tremor (21.6%) and weakness (18.1%) were the most common phenotypes. Compared with tremor (40.7 years), the mean ages at onset of dystonia (34.5 years) and weakness (36.4 years) were significantly younger, while gait disorders (43.2 years) had a significantly later age at onset. The interaction between gender and phenotype was not significant. FMD peaks in midlife with varying effects of gender on age at onset and phenotype. The data gives some support to 'lumping' FMD as a unitary disorder but also highlights the value in 'splitting' into individual phenotypes where relevant.
date: 2022-06
date_type: published
publisher: BMJ Publishing Group
official_url: https://doi.org/10.1136/jnnp-2021-328462
oa_status: green
full_text_type: other
language: eng
primo: open
primo_central: open_green
verified: verified_manual
elements_id: 1983733
doi: 10.1136/jnnp-2021-328462
medium: Print-Electronic
pii: jnnp-2021-328462
lyricists_name: Schrag, Anette
lyricists_id: AESCH71
actors_name: Schrag, Anette
actors_name: Taib, Linda
actors_id: AESCH71
actors_id: LTAIB41
actors_role: owner
actors_role: impersonator
funding_acknowledgements: [NHS Scotland NRS Career Fellowship]
full_text_status: public
publication: Journal of Neurology, Neurosurgery and Psychiatry
volume: 93
number: 6
pagerange: 609-616
event_location: England
citation:        Lidstone, Sarah C;    Costa-Parke, Michael;    Robinson, Emily J;    Ercoli, Tommaso;    Stone, Jon;    FMD GAP Study Group;      (2022)    Functional movement disorder gender, age and phenotype study: a systematic review and individual patient meta-analysis of 4905 cases.                   Journal of Neurology, Neurosurgery and Psychiatry , 93  (6)   pp. 609-616.    10.1136/jnnp-2021-328462 <https://doi.org/10.1136/jnnp-2021-328462>.       Green open access   
 
document_url: https://discovery.ucl.ac.uk/id/eprint/10163062/2/Schrag_FMD%20GAP%20manuscript_0128_Final%20%28003%29%20-%20AA-KL.pdf