eprintid: 10144750 rev_number: 6 eprint_status: archive userid: 699 dir: disk0/10/14/47/50 datestamp: 2022-03-08 11:39:52 lastmod: 2022-03-08 11:39:52 status_changed: 2022-03-08 11:39:52 type: article metadata_visibility: show sword_depositor: 699 creators_name: Sonustun, Berkiye creators_name: Altay, Melek Firat creators_name: Strand, Catherine creators_name: Ebanks, Kirsten creators_name: Hondhamuni, Geshanthi creators_name: Warner, Thomas T creators_name: Lashuel, Hilal A creators_name: Bandopadhyay, Rina title: Pathological Relevance of Post-Translationally Modified Alpha-Synuclein (pSer87, pSer129, nTyr39) in Idiopathic Parkinson’s Disease and Multiple System Atrophy ispublished: pub divisions: C07 divisions: F84 divisions: B02 divisions: UCL divisions: D07 keywords: alpha-synuclein; post-translational modifications; Parkinson’s disease; multiple system atrophy; Lewy bodies; Lewy neurites; glial cytoplasmic inclusions; phosphorylation; nitration; immunohistochemistry note: © 2022 by the authors. Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (https:// creativecommons.org/licenses/by/ 4.0/). abstract: Aggregated alpha-synuclein (α-synuclein) is the main component of Lewy bodies (LBs), Lewy neurites (LNs), and glial cytoplasmic inclusions (GCIs), which are pathological hallmarks of idiopathic Parkinson’s disease (IPD) and multiple system atrophy (MSA). Initiating factors that culminate in forming LBs/LNs/GCIs remain elusive. Several species of α-synuclein exist, including phosphorylated and nitrated forms. It is unclear which α-synuclein post-translational modifications (PTMs) appear within aggregates throughout disease pathology. Herein we aimed to establish the predominant α-synuclein PTMs in postmortem IPD and MSA pathology using immunohistochemistry. We examined the patterns of three α-synuclein PTMs (pS87, pS129, nY39) simultaneously in pathology-affected regions of 15 IPD cases, 5 MSA cases, and 6 neurologically normal controls. All antibodies recognized LBs, LNs, and GCIs, albeit to a variable extent. pS129 α-synuclein antibody was particularly immunopositive for LNs and synaptic dot-like structures, followed by nY39 α-synuclein antibody. GCIs, neuronal inclusions, and small threads were positive for nY39 α-synuclein in MSA. Quantification of the LB scores revealed that pS129 α-synuclein was the dominant and earliest α-synuclein PTM, followed by nY39 α-synuclein, while lower amounts of pSer87 α-synuclein appeared later in disease progression in PD. These results may have implications for novel biomarker and therapeutic developments. date: 2022-03-06 date_type: published publisher: MDPI AG official_url: https://doi.org/10.3390/cells11050906 oa_status: green full_text_type: pub language: eng primo: open primo_central: open_green verified: verified_manual elements_id: 1943754 doi: 10.3390/cells11050906 lyricists_name: Bandopadhyay, Rina lyricists_id: RBAND40 actors_name: Bandopadhyay, Rina actors_id: RBAND40 actors_role: owner full_text_status: public publication: Cells volume: 11 number: 5 article_number: 906 issn: 2073-4409 citation: Sonustun, Berkiye; Altay, Melek Firat; Strand, Catherine; Ebanks, Kirsten; Hondhamuni, Geshanthi; Warner, Thomas T; Lashuel, Hilal A; Sonustun, Berkiye; Altay, Melek Firat; Strand, Catherine; Ebanks, Kirsten; Hondhamuni, Geshanthi; Warner, Thomas T; Lashuel, Hilal A; Bandopadhyay, Rina; - view fewer <#> (2022) Pathological Relevance of Post-Translationally Modified Alpha-Synuclein (pSer87, pSer129, nTyr39) in Idiopathic Parkinson’s Disease and Multiple System Atrophy. Cells , 11 (5) , Article 906. 10.3390/cells11050906 <https://doi.org/10.3390/cells11050906>. Green open access document_url: https://discovery.ucl.ac.uk/id/eprint/10144750/1/cells-11-00906.pdf