eprintid: 10073714 rev_number: 23 eprint_status: archive userid: 608 dir: disk0/10/07/37/14 datestamp: 2019-05-15 13:48:38 lastmod: 2021-12-05 00:39:10 status_changed: 2019-05-15 13:48:38 type: article metadata_visibility: show creators_name: Younan, ND creators_name: Chen, K-F creators_name: Rose, R-S creators_name: Crowther, DC creators_name: Viles, JH title: Prion protein stabilizes amyloid-β (Aβ) oligomers and enhances Aβ neurotoxicity in a Drosophila model of Alzheimer's disease ispublished: pub divisions: UCL divisions: B02 divisions: C07 divisions: D07 divisions: F81 keywords: Alzheimer's disease, Drosophila, amyloid-beta (AB), animal model, circadian rhythm, fibril, neurodegenerative disease, oligomer, prion, protein misfolding, Alzheimer Disease, Amyloid, Amyloid beta-Peptides, Animals, Circadian Rhythm, Disease Models, Animal, Drosophila melanogaster, Longevity, Mesocricetus, Neurotoxicity Syndromes, Prion Proteins, Protein Binding, Protein Multimerization note: This version is the version of record. For information on re-use, please refer to the publisher’s terms and conditions. abstract: The cellular prion protein (PrPC) can act as a cell-surface receptor for β-amyloid (Aβ) peptide; however, a role for PrPC in the pathogenesis of Alzheimer's disease (AD) is contested. Here, we expressed a range of Aβ isoforms and PrPC in the Drosophila brain. We found that co-expression of Aβ and PrPC significantly reduces the lifespan, disrupts circadian rhythms, and increases Aβ deposition in the fly brain. In contrast, under the same conditions, expression of Aβ or PrPC individually did not lead to these phenotypic changes. In vitro studies revealed that substoichiometric amounts of PrPC trap Aβ as oligomeric assemblies and fragment-preformed Aβ fibers. The ability of membrane-anchored PrPC to trap Aβ as cytotoxic oligomers at the membrane surface and fragment inert Aβ fibers suggests a mechanism by which PrPC exacerbates Aβ deposition and pathogenic phenotypes in the fly, supporting a role for PrPC in AD. This study provides a second animal model linking PrPC expression with Aβ toxicity and supports a role for PrPC in AD pathogenesis. Blocking the interaction of Aβ and PrPC represents a potential therapeutic strategy. date: 2018-08-24 date_type: published official_url: https://doi.org/10.1074/jbc.RA118.003319 oa_status: green full_text_type: pub pmcid: PMC6109938 language: eng primo: open primo_central: open_green article_type_text: Journal Article verified: verified_manual elements_id: 1584272 doi: 10.1074/jbc.RA118.003319 pii: RA118.003319 lyricists_name: Chen, Ko-Fan lyricists_id: KCHEA78 actors_name: Allington-Smith, Dominic actors_id: DAALL44 actors_role: owner full_text_status: public publication: Journal of Biological Chemistry volume: 293 number: 34 pagerange: 13090-13099 event_location: United States issn: 1083-351X citation: Younan, ND; Chen, K-F; Rose, R-S; Crowther, DC; Viles, JH; (2018) Prion protein stabilizes amyloid-β (Aβ) oligomers and enhances Aβ neurotoxicity in a Drosophila model of Alzheimer's disease. Journal of Biological Chemistry , 293 (34) pp. 13090-13099. 10.1074/jbc.RA118.003319 <https://doi.org/10.1074/jbc.RA118.003319>. Green open access document_url: https://discovery.ucl.ac.uk/id/eprint/10073714/1/Chen_J.%20Biol.%20Chem.-2018-Younan-13090-9.pdf